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Expanded Newborn Screening for Inborn Errors of Metabolism in Hong Kong: Results and Outcome of a 7 Year Journey.
Belaramani, Kiran Moti; Chan, Toby Chun Hei; Hau, Edgar Wai Lok; Yeung, Matthew Chun Wing; Kwok, Anne Mei Kwun; Lo, Ivan Fai Man; Law, Terry Hiu Fung; Wu, Helen; Wong, Sheila Suet Na; Lam, Shirley Wai; Ha, Gladys Ha Yin; Lau, Toby Pui Yee; Wong, Tsz Ki; Or, Venus Wai Ching; Wong, Rosanna Ming Sum; Ming, Wong Lap; Chow, Jasmine Chi Kwan; Yau, Eric Kin Cheong; Fu, Antony; Chong, Josephine Shuk Ching; Yau, Ho Chung; Poon, Grace Wing Kit; Ng, Kwok Leung; Chan, Kwong Tat; Lam, Yuen Yu; Hui, Joannie; Mak, Chloe Miu; Fung, Cheuk Wing.
Afiliación
  • Belaramani KM; Metabolic Medicine Unit, Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Chan TCH; Newborn Screening Laboratory, Department of Pathology, Hong Kong Children's Hospital, Hong Kong, China.
  • Hau EWL; Clinical Genetics Service Unit, Hong Kong Children's Hospital, Hong Kong, China.
  • Yeung MCW; Newborn Screening Laboratory, Department of Pathology, Hong Kong Children's Hospital, Hong Kong, China.
  • Kwok AMK; Metabolic Medicine Unit, Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Lo IFM; Clinical Genetics Service Unit, Hong Kong Children's Hospital, Hong Kong, China.
  • Law THF; Metabolic Medicine Unit, Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Wu H; Metabolic Medicine Unit, Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Wong SSN; Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Lam SW; Metabolic Medicine Unit, Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Ha GHY; Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Lau TPY; Newborn Screening Laboratory, Department of Pathology, Hong Kong Children's Hospital, Hong Kong, China.
  • Wong TK; Newborn Screening Laboratory, Department of Pathology, Hong Kong Children's Hospital, Hong Kong, China.
  • Or VWC; Newborn Screening Laboratory, Department of Pathology, Hong Kong Children's Hospital, Hong Kong, China.
  • Wong RMS; Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Ming WL; Department of Paediatrics and Adolescent Medicine, Tuen Mun Hospital, Hong Kong, China.
  • Chow JCK; Department of Paediatrics and Adolescent Medicine, Queen Elizabeth Hospital, Hong Kong, China.
  • Yau EKC; Department of Paediatrics and Adolescent Medicine, Princess Margaret Hospital, Hong Kong, China.
  • Fu A; Department of Paediatrics and Adolescent Medicine, Princess Margaret Hospital, Hong Kong, China.
  • Chong JSC; Department of Paediatrics, The Chinese University of Hong Kong, Hong Kong, China.
  • Yau HC; Department of Paediatrics, Prince of Wales Hospital, Hong Kong, China.
  • Poon GWK; Department of Paediatrics and Adolescent Medicine, Queen Mary Hospital, Hong Kong, China.
  • Ng KL; Department of Paediatrics and Adolescent Medicine, United Christian Hospital, Hong Kong, China.
  • Chan KT; Department of Paediatrics and Adolescent Medicine, Pamela Youde Nethersole Eastern Hospital, Hong Kong, China.
  • Lam YY; Department of Paediatrics and Adolescent Medicine, Kwong Wah Hospital, Hong Kong, China.
  • Hui J; Metabolic Medicine Unit, Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
  • Mak CM; Newborn Screening Laboratory, Department of Pathology, Hong Kong Children's Hospital, Hong Kong, China.
  • Fung CW; Metabolic Medicine Unit, Department of Paediatrics and Adolescent Medicine, Hong Kong Children's Hospital, Hong Kong, China.
Int J Neonatal Screen ; 10(1)2024 Mar 11.
Article en En | MEDLINE | ID: mdl-38535127
ABSTRACT
Newborn screening (NBS) is an important public health program that aims to identify pre-symptomatic healthy babies that will develop significant disease if left undiagnosed and untreated. The number of conditions being screened globally is expanding rapidly in parallel with advances in technology, diagnosis, and treatment availability for these conditions. In Hong Kong, NBS for inborn errors of metabolism (NBSIEM) began as a pilot program in October 2015 and was implemented to all birthing hospitals within the public healthcare system in phases, with completion in October 2020. The number of conditions screened for increased from 21 to 24 in April 2016 and then to 26 in October 2019. The overall recruitment rate of the NBS program was 99.5%. In the period between October 2015 and December 2022, 125,688 newborns were screened and 295 were referred back for abnormal results. The recall rate was reduced from 0.26% to 0.12% after the implementation of second-tier testing. An inherited metabolic disorder (IMD) was eventually confirmed in 47 infants, making the prevalence of IMD in Hong Kong 1 in 2674. At the time of the NBS result, 78.7% of the newborns with IMD were asymptomatic. There were two deaths reported one newborn with methylmalonic acidemia cobalamin B type (MMACblB) died after the initial crisis and another case of carnitine palmitoyltransferase II deficiency (CPTII) died at 18 months of age after metabolic decompensation. The most common IMD noted were disorders of fatty acid oxidation metabolism (40%, 19 cases), closely followed by disorders of amino acid metabolism (38%, 18 cases), with carnitine uptake defect (19.1%, 9 cases) and citrullinemia type II (17%, 8 cases) being the two most common IMD picked up by the NBSIEM in Hong Kong. Out of the all the IMDs identified, 19.1% belonged to diverse ethnic groups. False negative cases were reported for citrullinemia type II and congenital adrenal hyperplasia during this period.
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Texto completo: 1 Colección: 01-internacional Base de datos: MEDLINE Idioma: En Revista: Int J Neonatal Screen Año: 2024 Tipo del documento: Article País de afiliación: China Pais de publicación: Suiza

Texto completo: 1 Colección: 01-internacional Base de datos: MEDLINE Idioma: En Revista: Int J Neonatal Screen Año: 2024 Tipo del documento: Article País de afiliación: China Pais de publicación: Suiza